Actin Nemaline Myopathy Mouse Reproduces disease, suggests other actin disease phenotypes and provides cautionary note on muscle transgene expression

Mutations in the skeletal muscle a-actin gene (ACTA1) cause congenital myopathies including nemaline myopathy, actin aggregate myopathy and rod-core disease. The majority of patients with ACTA1 mutations have severe hypotonia and do not survive beyond the age of one. A transgenic mouse model was gen...

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Bibliographic Details
Main Authors: Ravenscroft, G., Jackaman, Connie, Sewry, C., Mcnamara, E., Squire, S., Potter, A., Papadimitriou, J., Griffiths, L., Bakker, A., Davies, K., Laing, N., Nowak, K.
Format: Journal Article
Published: Public Library of Science 2011
Online Access:http://hdl.handle.net/20.500.11937/49290