A Case of Necrotizing Keratoscleritis in Primary Sjogren's Syndrome

We report on a case of necrotizing keratoscleritis in primary Sjogren's syndrome. A 66-year-old female patient who was complaining of ocular pain, tearing and decreased vision in her right eye for the previous two days was admitted to our hospital. Visual acuity in the right eye was hand moveme...

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Main Authors:	Choi, Won, Lee, Shin-Seok, Park, Yeong-Geol, Yoon, Kyung-Chul
Format:	Online
Language:	English
Published:	The Korean Ophthalmological Society 2011
Online Access:	https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3149140/

id	pubmed-3149140
recordtype	oai_dc
spelling	pubmed-31491402011-08-22 A Case of Necrotizing Keratoscleritis in Primary Sjogren's Syndrome Choi, Won Lee, Shin-Seok Park, Yeong-Geol Yoon, Kyung-Chul Case Report We report on a case of necrotizing keratoscleritis in primary Sjogren's syndrome. A 66-year-old female patient who was complaining of ocular pain, tearing and decreased vision in her right eye for the previous two days was admitted to our hospital. Visual acuity in the right eye was hand movement, and initial examination showed a 3.0 × 1.8 mm uveal mass bulging through a corneoscleral melting site in the nasal region of the right eye. Positive anti-nuclear antibody was identified at a titer of 1:320 with a speckled pattern, and both Sjogren's syndrome A and Sjogren's syndrome B antibody tests were positive, with titers >200 U/mL. A technetium 99m pertechnetate salivary scan revealed chronic sialoadenitis in the submandibular glands. We diagnosed the lesion as necrotizing keratoscleritis due to primary Sjogren's syndrome. A corneoscleral patch graft was performed, followed by immunosuppression including oral cyclosporin and topical prednisolone. During a follow-up period of 12 months, the corneoscleral graft was well maintained with no recurrence. The Korean Ophthalmological Society 2011-08 2011-07-22 /pmc/articles/PMC3149140/ /pubmed/21860576 http://dx.doi.org/10.3341/kjo.2011.25.4.275 Text en © 2011 The Korean Ophthalmological Society http://creativecommons.org/licenses/by-nc/3.0/ This is an Open Access article distributed under the terms of the Creative Commons Attribution Non-Commercial License (http://creativecommons.org/licenses/by-nc/3.0/) which permits unrestricted non-commercial use, distribution, and reproduction in any medium, provided the original work is properly cited.
repository_type	Open Access Journal
institution_category	Foreign Institution
institution	US National Center for Biotechnology Information
building	NCBI PubMed
collection	Online Access
language	English
format	Online
author	Choi, Won Lee, Shin-Seok Park, Yeong-Geol Yoon, Kyung-Chul
spellingShingle	Choi, Won Lee, Shin-Seok Park, Yeong-Geol Yoon, Kyung-Chul A Case of Necrotizing Keratoscleritis in Primary Sjogren's Syndrome
author_facet	Choi, Won Lee, Shin-Seok Park, Yeong-Geol Yoon, Kyung-Chul
author_sort	Choi, Won
title	A Case of Necrotizing Keratoscleritis in Primary Sjogren's Syndrome
title_short	A Case of Necrotizing Keratoscleritis in Primary Sjogren's Syndrome
title_full	A Case of Necrotizing Keratoscleritis in Primary Sjogren's Syndrome
title_fullStr	A Case of Necrotizing Keratoscleritis in Primary Sjogren's Syndrome
title_full_unstemmed	A Case of Necrotizing Keratoscleritis in Primary Sjogren's Syndrome
title_sort	case of necrotizing keratoscleritis in primary sjogren's syndrome
description	We report on a case of necrotizing keratoscleritis in primary Sjogren's syndrome. A 66-year-old female patient who was complaining of ocular pain, tearing and decreased vision in her right eye for the previous two days was admitted to our hospital. Visual acuity in the right eye was hand movement, and initial examination showed a 3.0 × 1.8 mm uveal mass bulging through a corneoscleral melting site in the nasal region of the right eye. Positive anti-nuclear antibody was identified at a titer of 1:320 with a speckled pattern, and both Sjogren's syndrome A and Sjogren's syndrome B antibody tests were positive, with titers >200 U/mL. A technetium 99m pertechnetate salivary scan revealed chronic sialoadenitis in the submandibular glands. We diagnosed the lesion as necrotizing keratoscleritis due to primary Sjogren's syndrome. A corneoscleral patch graft was performed, followed by immunosuppression including oral cyclosporin and topical prednisolone. During a follow-up period of 12 months, the corneoscleral graft was well maintained with no recurrence.
publisher	The Korean Ophthalmological Society
publishDate	2011
url	https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3149140/
_version_	1611468910697119744

A Case of Necrotizing Keratoscleritis in Primary Sjogren's Syndrome

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