Diverse Sphingolipid Species Harbor Different Effects on Ire1 Clustering

Endoplasmic reticulum (ER) function is dedicated to multiple essential processes in eukaryotes, including the processing of secretory proteins and the biogenesis of most membrane lipids. These roles implicate a heavy burden to the organelle, and it is thus prone to fluctuations in the homeostasis of...

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Main Authors: Bieniawski, Mark A., Stevens, Kofi L.P., Witham, Christopher M., Steuart, Robert F. L., Bankaitis, V.A., Mousley, Carl J.
Format: Journal Article
Language:English
Published: MDPI 2022
Subjects:
Online Access:http://hdl.handle.net/20.500.11937/96046
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author Bieniawski, Mark A.
Stevens, Kofi L.P.
Witham, Christopher M.
Steuart, Robert F. L.
Bankaitis, V.A.
Mousley, Carl J.
author_facet Bieniawski, Mark A.
Stevens, Kofi L.P.
Witham, Christopher M.
Steuart, Robert F. L.
Bankaitis, V.A.
Mousley, Carl J.
author_sort Bieniawski, Mark A.
building Curtin Institutional Repository
collection Online Access
description Endoplasmic reticulum (ER) function is dedicated to multiple essential processes in eukaryotes, including the processing of secretory proteins and the biogenesis of most membrane lipids. These roles implicate a heavy burden to the organelle, and it is thus prone to fluctuations in the homeostasis of molecules which govern these processes. The unfolded protein response (UPR) is a general ER stress response tasked with maintaining the ER for optimal function, mediated by the master activator Ire1. Ire1 is an ER transmembrane protein that initiates the UPR, forming characteristic oligomers in response to irregularities in luminal protein folding and in the membrane lipid environment. The role of lipids in regulating the UPR remains relatively obscure; however, recent research has revealed a potent role for sphingolipids in its activity. Here, we identify a major role for the oxysterol-binding protein Kes1, whose activity is of consequence to the sphingolipid profile in cells resulting in an inhibition of UPR activity. Using an mCherry-tagged derivative of Ire1, we observe that this occurs due to inhibition of Ire1 to form oligomers. Furthermore, we identify that a sphingolipid presence is required for Ire1 activity, and that specific sphingolipid profiles are of major consequence to Ire1 function. In addition, we highlight cases where Ire1 oligomerization is absent despite an active UPR, revealing a potential mechanism for UPR induction where Ire1 oligomerization is not necessary. This work provides a basis for the role of sphingolipids in controlling the UPR, where their metabolism harbors a crucial role in regulating its onset.
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spelling curtin-20.500.11937-960462024-12-05T01:14:05Z Diverse Sphingolipid Species Harbor Different Effects on Ire1 Clustering Bieniawski, Mark A. Stevens, Kofi L.P. Witham, Christopher M. Steuart, Robert F. L. Bankaitis, V.A. Mousley, Carl J. Science & Technology Life Sciences & Biomedicine Physical Sciences Biochemistry & Molecular Biology Chemistry, Multidisciplinary Chemistry unfolded protein response (UPR) Ire1 sphingolipids Kes1 Osh4 UNFOLDED PROTEIN RESPONSE STRESS SENSOR IRE1 SACCHAROMYCES METABOLISM ACTIVATION CERAMIDES MECHANISM STRAINS SIGNALS BINDING Ire1 Kes1 Osh4 sphingolipids unfolded protein response (UPR) Protein Serine-Threonine Kinases Sphingolipids Unfolded Protein Response Endoplasmic Reticulum Stress Cluster Analysis Oxysterols Endoribonucleases Endoribonucleases Sphingolipids Cluster Analysis Unfolded Protein Response Endoplasmic Reticulum Stress Oxysterols Protein Serine-Threonine Kinases Endoplasmic reticulum (ER) function is dedicated to multiple essential processes in eukaryotes, including the processing of secretory proteins and the biogenesis of most membrane lipids. These roles implicate a heavy burden to the organelle, and it is thus prone to fluctuations in the homeostasis of molecules which govern these processes. The unfolded protein response (UPR) is a general ER stress response tasked with maintaining the ER for optimal function, mediated by the master activator Ire1. Ire1 is an ER transmembrane protein that initiates the UPR, forming characteristic oligomers in response to irregularities in luminal protein folding and in the membrane lipid environment. The role of lipids in regulating the UPR remains relatively obscure; however, recent research has revealed a potent role for sphingolipids in its activity. Here, we identify a major role for the oxysterol-binding protein Kes1, whose activity is of consequence to the sphingolipid profile in cells resulting in an inhibition of UPR activity. Using an mCherry-tagged derivative of Ire1, we observe that this occurs due to inhibition of Ire1 to form oligomers. Furthermore, we identify that a sphingolipid presence is required for Ire1 activity, and that specific sphingolipid profiles are of major consequence to Ire1 function. In addition, we highlight cases where Ire1 oligomerization is absent despite an active UPR, revealing a potential mechanism for UPR induction where Ire1 oligomerization is not necessary. This work provides a basis for the role of sphingolipids in controlling the UPR, where their metabolism harbors a crucial role in regulating its onset. 2022 Journal Article http://hdl.handle.net/20.500.11937/96046 10.3390/ijms232012130 English http://creativecommons.org/licenses/by/4.0/ MDPI fulltext
spellingShingle Science & Technology
Life Sciences & Biomedicine
Physical Sciences
Biochemistry & Molecular Biology
Chemistry, Multidisciplinary
Chemistry
unfolded protein response (UPR)
Ire1
sphingolipids
Kes1
Osh4
UNFOLDED PROTEIN RESPONSE
STRESS SENSOR IRE1
SACCHAROMYCES
METABOLISM
ACTIVATION
CERAMIDES
MECHANISM
STRAINS
SIGNALS
BINDING
Ire1
Kes1
Osh4
sphingolipids
unfolded protein response (UPR)
Protein Serine-Threonine Kinases
Sphingolipids
Unfolded Protein Response
Endoplasmic Reticulum Stress
Cluster Analysis
Oxysterols
Endoribonucleases
Endoribonucleases
Sphingolipids
Cluster Analysis
Unfolded Protein Response
Endoplasmic Reticulum Stress
Oxysterols
Protein Serine-Threonine Kinases
Bieniawski, Mark A.
Stevens, Kofi L.P.
Witham, Christopher M.
Steuart, Robert F. L.
Bankaitis, V.A.
Mousley, Carl J.
Diverse Sphingolipid Species Harbor Different Effects on Ire1 Clustering
title Diverse Sphingolipid Species Harbor Different Effects on Ire1 Clustering
title_full Diverse Sphingolipid Species Harbor Different Effects on Ire1 Clustering
title_fullStr Diverse Sphingolipid Species Harbor Different Effects on Ire1 Clustering
title_full_unstemmed Diverse Sphingolipid Species Harbor Different Effects on Ire1 Clustering
title_short Diverse Sphingolipid Species Harbor Different Effects on Ire1 Clustering
title_sort diverse sphingolipid species harbor different effects on ire1 clustering
topic Science & Technology
Life Sciences & Biomedicine
Physical Sciences
Biochemistry & Molecular Biology
Chemistry, Multidisciplinary
Chemistry
unfolded protein response (UPR)
Ire1
sphingolipids
Kes1
Osh4
UNFOLDED PROTEIN RESPONSE
STRESS SENSOR IRE1
SACCHAROMYCES
METABOLISM
ACTIVATION
CERAMIDES
MECHANISM
STRAINS
SIGNALS
BINDING
Ire1
Kes1
Osh4
sphingolipids
unfolded protein response (UPR)
Protein Serine-Threonine Kinases
Sphingolipids
Unfolded Protein Response
Endoplasmic Reticulum Stress
Cluster Analysis
Oxysterols
Endoribonucleases
Endoribonucleases
Sphingolipids
Cluster Analysis
Unfolded Protein Response
Endoplasmic Reticulum Stress
Oxysterols
Protein Serine-Threonine Kinases
url http://hdl.handle.net/20.500.11937/96046